A Comprehensive, Ethnically Diverse Library of Sickle Cell Disease-Specific Induced Pluripotent Stem Cells

Stem Cell Reports. 2017 Apr 11;8(4):1076-1085. doi: 10.1016/j.stemcr.2016.12.017. Epub 2017 Jan 19.

Abstract

Sickle cell anemia affects millions of people worldwide and is an emerging global health burden. As part of a large NIH-funded NextGen Consortium, we generated a diverse, comprehensive, and fully characterized library of sickle-cell-disease-specific induced pluripotent stem cells (iPSCs) from patients of different ethnicities, β-globin gene (HBB) haplotypes, and fetal hemoglobin (HbF) levels. iPSCs stand to revolutionize the way we study human development, model disease, and perhaps eventually, treat patients. Here, we describe this unique resource for the study of sickle cell disease, including novel haplotype-specific polymorphisms that affect disease severity, as well as for the development of patient-specific therapeutics for this phenotypically diverse disorder. As a complement to this library, and as proof of principle for future cell- and gene-based therapies, we also designed and employed CRISPR/Cas gene editing tools to correct the sickle hemoglobin (HbS) mutation.

Keywords: directed differentiation; disease modeling; gene correction; iPSCs; induced pluripotent stem cells; sickle cell disease.

Publication types

  • Research Support, Non-U.S. Gov't
  • Research Support, N.I.H., Extramural

MeSH terms

  • Adolescent
  • Adult
  • Anemia, Sickle Cell / blood
  • Anemia, Sickle Cell / ethnology
  • Anemia, Sickle Cell / genetics*
  • Anemia, Sickle Cell / therapy*
  • Base Sequence
  • CRISPR-Cas Systems*
  • Cell Line
  • Cells, Cultured
  • Child
  • Child, Preschool
  • Erythroid Cells / cytology
  • Erythroid Cells / metabolism
  • Female
  • Fetal Hemoglobin / analysis
  • Genetic Therapy* / methods
  • Haplotypes
  • Hemoglobin, Sickle / genetics*
  • Humans
  • Induced Pluripotent Stem Cells / cytology
  • Induced Pluripotent Stem Cells / metabolism*
  • Male
  • Middle Aged
  • Point Mutation
  • Polymorphism, Genetic
  • Transcriptome
  • Young Adult
  • beta-Globins / genetics*

Substances

  • Hemoglobin, Sickle
  • beta-Globins
  • Fetal Hemoglobin