Identification of a novel nonsense mutation of the neurotrophic tyrosine kinase receptor type 1 gene in two siblings with congenital insensitivity to pain with anhidrosis

J Int Med Res. 2017 Apr;45(2):549-555. doi: 10.1177/0300060517691699. Epub 2017 Mar 27.

Abstract

Objective To explore the aetiology of congenital insensitivity to pain with anhidrosis (CIPA) in two Chinese siblings with typical CIPA symptoms including insensitivity to pain, inability to sweat, and self-mutilating behaviours. Methods Clinical examination and genetic testing were conducted of all available family members, and the findings were used to create a pedigree. Mutation screening using PCR amplification and DNA Sanger sequencing of the entire neurotrophic tyrosine kinase receptor type 1 gene ( NTRK1) including intron-exon boundaries was used to identify mutations associated with CIPA. Results A novel nonsense mutation (c.7C > T, p. Arg3Ter) and a known splice-site mutation (c.851-33 T > A) were detected in NTRK1 and shown to be associated with CIPA. Conclusion Our findings expand the known mutation spectrum of NTRK1 and provide insights into the aetiology of CIPA.

Keywords: Congenital insensitivity to pain with anhidrosis; NTRK1; hereditary sensory and autonomic neuropathy type IV; mutation.

Publication types

  • Case Reports

MeSH terms

  • Adolescent
  • Child
  • Exons
  • Gene Expression
  • Hereditary Sensory and Autonomic Neuropathies / genetics*
  • Hereditary Sensory and Autonomic Neuropathies / physiopathology
  • Hereditary Sensory and Autonomic Neuropathies / psychology
  • Humans
  • Hypohidrosis / genetics*
  • Hypohidrosis / physiopathology
  • Introns
  • Male
  • Mutation*
  • Pedigree
  • Receptor, trkA / genetics*
  • Self Mutilation / genetics*
  • Self Mutilation / physiopathology
  • Self Mutilation / psychology
  • Sequence Analysis, DNA
  • Siblings

Substances

  • Receptor, trkA