Risk factors for heart disease in transfusion-dependent thalassemia: serum ferritin revisited

Intern Emerg Med. 2019 Apr;14(3):365-370. doi: 10.1007/s11739-018-1890-2. Epub 2018 Jun 12.

Abstract

Heart disease remains a leading cause of morbidity and mortality in transfusion-dependent thalassemia (TDT), which can be attributed to several factors but primarily develops in the setting of iron overload. This was a retrospective cohort study utilizing Webthal® patient data from five major centers across Italy. Patients without heart disease were followed-up for 10 years (2000-2010) and data were collected for demographics, splenectomy status, serum ferritin and hemoglobin levels, and comorbidities associated with heart disease. Among 379 patients analyzed (mean age 22.9 ± 5.1 years, 47.8% men), 44 (cumulative incidence: 11.6%) developed heart disease during the period of observation. Splenectomy (p = 0.002) and serum ferritin level (p < 0.001) were the only risk factors with significant association with heart disease. A serum ferritin threshold of ≥ 3000 ng/mL was the best predictor for the development of heart disease (86.4% sensitivity and 92.8% specificity, AUC: 0.912, 95% CI 0.852-0.971, p < 0.001). On multivariate analysis, only a serum ferritin level ≥ 3000 ng/mL remained significantly and independently associated with increased risk of heart disease (HR: 44.85, 95% CI 18.85-106.74), with a 5- and 10-year heart disease-free survival of 58 and 39%. The association between iron overload and heart disease in patients with TDT is confirmed, yet a new serum ferritin level of 3000 ng/mL to flag increased risk is suggested.

Keywords: Heart disease; Iron overload; Serum ferritin; Thalassemia.

Publication types

  • Multicenter Study

MeSH terms

  • Adolescent
  • Adult
  • Area Under Curve
  • Blood Transfusion / methods
  • Blood Transfusion / trends
  • Chi-Square Distribution
  • Child
  • Cohort Studies
  • Female
  • Ferritins / adverse effects
  • Ferritins / analysis*
  • Ferritins / blood
  • Heart Diseases / complications*
  • Heart Diseases / physiopathology
  • Humans
  • Italien
  • Male
  • ROC Curve
  • Retrospective Studies
  • Risk Factors
  • Survival Analysis
  • Thalassemia / complications*
  • Thalassemia / physiopathology
  • Thalassemia / therapy*

Substances

  • Ferritins