EWSR1-FLI1 Activation of the Cancer/Testis Antigen FATE1 Promotes Ewing Sarcoma Survival

Mol Cell Biol. 2019 Jun 27;39(14):e00138-19. doi: 10.1128/MCB.00138-19. Print 2019 Jul 15.

Abstract

Ewing sarcoma is characterized by a pathognomonic chromosomal translocation that generates the EWSR1-FLI1 chimeric transcription factor. The transcriptional targets of EWSR1-FLI1 that are essential for tumorigenicity are incompletely defined. Here, we found that EWSR1-FLI1 modulates the expression of cancer/testis (CT) antigen genes, whose expression is biased to the testes but is also activated in cancer. Among these CT antigens, fetal and adult testis expressed 1 (FATE1) is most robustly induced. EWSR1-FLI1 associates with the GGAA repeats in the proximal promoter of FATE1, which exhibits accessible chromatin exclusively in mesenchymal progenitor cells (MPCs) and Ewing sarcoma cells. Expression of EWSR1-FLI1 in non-Ewing sarcoma cells and in MPCs enhances FATE1 mRNA and protein expression. Conversely, depletion of EWSR1-FLI1 in Ewing sarcoma cells leads to a loss of FATE1 expression. Importantly, we found that FATE1 is required for survival and anchorage-independent growth in Ewing sarcoma cells via attenuating the accumulation of BNIP3L, a BH3-only protein that is toxic when stabilized. This action appears to be mediated by the E3 ligase RNF183. We propose that engaging FATE1 function can permit the bypass of cell death mechanisms that would otherwise inhibit tumor progression.

Keywords: BNIP3L; CT antigen; EWSR1-FLI1; Ewing sarcoma; FATE1; RNF183; cancer/testis antigen.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Bone Neoplasms / genetics*
  • Bone Neoplasms / metabolism
  • Cell Line, Tumor
  • Cell Survival
  • DNA-Binding Proteins / genetics*
  • DNA-Binding Proteins / metabolism
  • Gene Expression Regulation, Neoplastic
  • HeLa Cells
  • Hep G2 Cells
  • Humans
  • Membrane Proteins / metabolism
  • Oncogene Proteins, Fusion / genetics*
  • Promoter Regions, Genetic
  • Proto-Oncogene Proteins / metabolism
  • Sarcoma, Ewing / genetics*
  • Sarcoma, Ewing / metabolism
  • Transcription Factors / genetics*
  • Transcription Factors / metabolism
  • Tumor Suppressor Proteins / metabolism
  • Ubiquitin-Protein Ligases / metabolism

Substances

  • BNIP3L protein, human
  • DNA-Binding Proteins
  • EWSR1-FLI1 fusion protein, human
  • FATE1 protein, human
  • Membrane Proteins
  • Oncogene Proteins, Fusion
  • Proto-Oncogene Proteins
  • Transcription Factors
  • Tumor Suppressor Proteins
  • RNF183 protein, human
  • Ubiquitin-Protein Ligases