A fast and powerful aggregated Cauchy association test for joint analysis of multiple phenotypes

Genes Genomics. 2021 Jan;43(1):69-77. doi: 10.1007/s13258-020-01034-3. Epub 2021 Jan 11.

Abstract

Background: Pleiotropy is a widespread phenomenon in complex human diseases. Jointly analyzing multiple phenotypes can improve power performance of detecting genetic variants and uncover the underlying genetic mechanism.

Objective: This study aims to detect the association between genetic variants in a genomic region and multiple phenotypes.

Methods: We develop the aggregated Cauchy association test to detect the association between rare variants in a genomic region and multiple phenotypes (abbreviated as "Multi-ACAT"). Multi-ACAT first detects the association between each rare variant and multiple phenotypes based on reverse regression and obtains variant-level p-values, then takes linear combination of transformed p-values as the test statistic which approximately follows Cauchy distribution under the null hypothesis.

Results: Extensive simulation studies show that when the proportion of causal variants in a genomic region is extremely small, Multi-ACAT is more powerful than the other several methods and is robust to bi-directional effects of causal variants. Finally, we illustrate our proposed method by analyzing two phenotypes [systolic blood pressure (SBP) and diastolic blood pressure (DBP)] from Genetic Analysis Workshop 19 (GAW19).

Conclusion: The Multi-ACAT computes extremely fast, does not consider complex distributions of multiple correlated phenotypes, and can be applied to the case with noise phenotypes.

Keywords: Association analysis; Multiple phenotypes; Pleiotropy; Rare variant.

Publication types

  • Research Support, N.I.H., Extramural
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Algorithms
  • Blood Pressure / genetics
  • Genetic Pleiotropy*
  • Genome-Wide Association Study / methods*
  • Humans
  • Polymorphism, Genetic