Tandem autologous hematopoietic stem cell transplantation for embryonal brain tumors in infants and very young children

Bone Marrow Transplant. 2022 Apr;57(4):607-612. doi: 10.1038/s41409-022-01593-x. Epub 2022 Feb 3.

Abstract

Withdrawal of radiotherapy in patients with brain tumors under four years decreases chance for cure. AutoHSCT in a series of pilot studies demonstrated a potential to improve outcomes in these patients. The study included 50 patients with median age of 39 months (7-53). Medulloblastoma (n = 28, 56%), ETMR (n = 9, 18%) and other histological types (n = 13, 26%) were most commonly diagnosed. Forty two patients (84%) received tandem autoHSCT by HIT-MED protocol, and single autoHSCT was performed in eight children (16%). Adjuvant radiotherapy was administered in 25 (50%) children and treatment of relapse included radiotherapy in 6 (12%). Median follow-up was 39.6 months (6-121). Long-term CIR was 37%, and TRM - 6%. Five-year OS was 71% in medulloblastoma, 37% in ETMR and in other tumors - 51% (p = 0.07). Irradiation-free OS at 5 years for children with medulloblastoma was 24%. For the whole cohort of CNS tumors, independently of histology, OS and PFS at five years were 60% and 46%, respectively Young children with medulloblastoma, following tandem autoHSCT, demonstrate OS comparable to older children. Patients with other histological types demonstrate suboptimal long-term survival rates after autoHSCT and one should assess whether these patients benefit from autoHSCT.

MeSH terms

  • Adolescent
  • Antineoplastic Combined Chemotherapy Protocols / adverse effects
  • Brain Neoplasms* / therapy
  • Cerebellar Neoplasms* / etiology
  • Cerebellar Neoplasms* / therapy
  • Child
  • Child, Preschool
  • Hematopoietic Stem Cell Transplantation*
  • Humans
  • Infant
  • Medulloblastoma* / drug therapy
  • Neoplasm Recurrence, Local
  • Transplantation, Autologous
  • Treatment Outcome