Incidence and Prevalence of Children's Diffuse Lung Disease in Spain
Arch Bronconeumol. 2022 Jan;58(1):22-29.
doi: 10.1016/j.arbres.2021.06.001.
Epub 2021 Jun 17.
[Article in
English,
Spanish]
Authors
Alba Torrent-Vernetta
1
, Mirella Gaboli
2
, Silvia Castillo-Corullón
3
, Pedro Mondéjar-López
4
, Verónica Sanz Santiago
5
, Jordi Costa-Colomer
6
, Borja Osona
7
, Javier Torres-Borrego
8
, Olga de la Serna-Blázquez
9
, Sara Bellón Alonso
10
, Pilar Caro Aguilera
11
, Álvaro Gimeno-Díaz de Atauri
12
, Alfredo Valenzuela Soria
13
, Roser Ayats
14
, Carlos Martin de Vicente
15
, Valle Velasco González
16
, José Domingo Moure González
17
, Elisa María Canino Calderín
18
, María Dolores Pastor-Vivero
19
, María Ángeles Villar Álvarez
20
, Sandra Rovira-Amigo
1
, Ignacio Iglesias Serrano
21
, Ana Díez Izquierdo
21
, Inés de Mir Messa
21
, Silvia Gartner
21
, Alexandra Navarro
22
, Noelia Baz-Redón
23
, Rosario Carmona
24
, Núria Camats-Tarruella
25
, Mónica Fernández-Cancio
25
, Christina Rapp
26
, Joaquin Dopazo
27
, Matthias Griese
26
, Antonio Moreno-Galdó
28
; ChILD-Spain Group
Affiliations
- 1 Paediatric Allergy and Pulmonology Section, Department of Paediatrics, Vall d'Hebron Hospital Universitari, Vall d'Hebron Barcelona Hospital Campus, Universitat Autònoma de Barcelona, Spain; Vall d'Hebron Institut de Recerca (VHIR), Hospital Universitari Vall d'Hebron, Barcelona, Spain; Department of Paediatrics, Obstetrics, Gynecology, Preventative Medicine and Public Health, Universitat Autònoma de Barcelona, Bellaterra, Barcelona, Spain; Center for Biomedical Research on Rare Diseases (CIBERER), Instituto de Salud Carlos III, Spain.
- 2 Paediatric Allergy and Pulmonology Section, Department of Paediatrics, University Hospital Virgen del Rocío, Sevilla, Spain.
- 3 Paediatric Pulmonology and Cystic Fibrosis Department, Hospital Clínico Universitario de Valencia, Spain.
- 4 Paediatric Pulmonology and Cystic Fibrosis Unit, University Clinic Virgen de la Arrixaca Hospital, University of Murcia, Spain.
- 5 Paediatric Pulmonology and Cystic Fibrosis Department, Hospital Universitario Infantil Niño Jesús, Madrid, Spain.
- 6 Paediatric Pulmonology and Cystic Fibrosis Department, Hospital Sant Joan de Déu, Barcelona, Spain.
- 7 Paediatric Pulmonology and Allergology Department, Hospital Universitario Son Espases, Palma de Mallorca, Spain.
- 8 Hospital Universitario Reina Sofía, Córdoba, Spain.
- 9 Paediatric Pulmonology Department, Hospital Universitario La Paz, Madrid, Spain.
- 10 Paediatric Pulmonology Department, Paediatrics Department, Hospital Universitario Gregorio Marañón, Madrid, Spain.
- 11 Paediatric Pulmonology Department, Hospital Regional Universitario de Málaga, IBIMA, Spain.
- 12 Paediatric Pulmonology and Allergology Department, 12 de Octubre University Hospital, Madrid, Spain.
- 13 Paediatric Pulmonology Department, Hospital Universitario Virgen de las Nieves, Granada, Spain.
- 14 Paediatric Pulmonology and Allergology Department, Parc Taulí Hospital Universitari, Institut d'Investigació i Innovació Parc Taulí I3PT, Sabadell, Universitat Autònoma de Barcelona, Barcelona, Spain.
- 15 Paediatric Pulmonology Department, Hospital Universitario Miguel Servet, Zaragoza, Spain.
- 16 Paediatric Pulmonology Department, Hospital Universitario de Canarias, Tenerife, Spain.
- 17 Paediatric Pulmonology and Allergology Department, Paediatrics Department, Hospital Clínico Universitario de Santiago, Spain.
- 18 Paediatric Pulmonology Department, Hospital Universitario Materno Infantil Canarias, Las Palmas de Gran Canaria, Spain.
- 19 Paediatric Pulmonology Department, Hospital Universitario Cruces, IIS Biocruces Bizkaia, Barakaldo, Bizkaia, Spain.
- 20 Paediatric Pulmonology Department, Hospital Universitario Basurto, Bilbao, Spain.
- 21 Paediatric Allergy and Pulmonology Section, Department of Paediatrics, Vall d'Hebron Hospital Universitari, Vall d'Hebron Barcelona Hospital Campus, Universitat Autònoma de Barcelona, Spain; Vall d'Hebron Institut de Recerca (VHIR), Hospital Universitari Vall d'Hebron, Barcelona, Spain; Department of Paediatrics, Obstetrics, Gynecology, Preventative Medicine and Public Health, Universitat Autònoma de Barcelona, Bellaterra, Barcelona, Spain.
- 22 Pathology Department, Vall d'Hebron Hospital Universitari, Vall d'Hebron Barcelona Hospital Campus, Universitat Autònoma de Barcelona, Spain.
- 23 Vall d'Hebron Institut de Recerca (VHIR), Hospital Universitari Vall d'Hebron, Barcelona, Spain; Department of Paediatrics, Obstetrics, Gynecology, Preventative Medicine and Public Health, Universitat Autònoma de Barcelona, Bellaterra, Barcelona, Spain.
- 24 Clinical Bioinformatics Area, Fundación Progreso y Salud (FPS), CDCA, University Hospital Virgen del Rocío, Sevilla, Spain.
- 25 Vall d'Hebron Institut de Recerca (VHIR), Hospital Universitari Vall d'Hebron, Barcelona, Spain; Department of Paediatrics, Obstetrics, Gynecology, Preventative Medicine and Public Health, Universitat Autònoma de Barcelona, Bellaterra, Barcelona, Spain; Center for Biomedical Research on Rare Diseases (CIBERER), Instituto de Salud Carlos III, Spain.
- 26 Division of Pediatric Pneumology, Dr. von Hauner Children's Hospital, University Hospital Munich, Germany.
- 27 Clinical Bioinformatics Area, Fundación Progreso y Salud (FPS), CDCA, University Hospital Virgen del Rocío, Sevilla, Spain; Computational Systems Medicine, Institute of Biomedicine of Seville (IBIS), Bioinformatics in Rare Diseases (BiER), Centro de Investigación Biomédica en Red de Enfermedades Raras (CIBERER), FPS, Functional Genomics Node (INB), FPS, University Hospital Virgen del Rocío, Sevilla, Spain.
- 28 Paediatric Allergy and Pulmonology Section, Department of Paediatrics, Vall d'Hebron Hospital Universitari, Vall d'Hebron Barcelona Hospital Campus, Universitat Autònoma de Barcelona, Spain; Vall d'Hebron Institut de Recerca (VHIR), Hospital Universitari Vall d'Hebron, Barcelona, Spain; Department of Paediatrics, Obstetrics, Gynecology, Preventative Medicine and Public Health, Universitat Autònoma de Barcelona, Bellaterra, Barcelona, Spain; Center for Biomedical Research on Rare Diseases (CIBERER), Instituto de Salud Carlos III, Spain. Electronic address: [email protected].
Abstract
Background:
Children's diffuse lung disease, also known as children's Interstitial Lung Diseases (chILD), are a heterogeneous group of rare diseases with relevant morbidity and mortality, which diagnosis and classification are very complex. Epidemiological data are scarce. The aim of this study was to analyse incidence and prevalence of chILD in Spain.
Methods:
Multicentre observational prospective study in patients from 0 to 18 years of age with chILD to analyse its incidence and prevalence in Spain, based on data reported in 2018 and 2019.
Results:
A total of 381 cases with chILD were notified from 51 paediatric pulmonology units all over Spain, covering the 91.7% of the paediatric population. The average incidence of chILD was 8.18 (CI 95% 6.28-10.48) new cases/million of children per year. The average prevalence of chILD was 46.53 (CI 95% 41.81-51.62) cases/million of children. The age group with the highest prevalence were children under 1 year of age. Different types of disorders were seen in children 2-18 years of age compared with children 0-2 years of age. Most frequent cases were: primary pulmonary interstitial glycogenosis in neonates (17/65), neuroendocrine cell hyperplasia of infancy in infants from 1 to 12 months (44/144), idiopathic pulmonary haemosiderosis in children from 1 to 5 years old (13/74), hypersensitivity pneumonitis in children from 5 to 10 years old (9/51), and scleroderma in older than 10 years old (8/47).
Conclusions:
We found a higher incidence and prevalence of chILD than previously described probably due to greater understanding and increased clinician awareness of these rare diseases.
Keywords:
Childhood interstitial lung disease; Children; Children's Interstitial Lung disease; Diffuse lung disease; Enfermedad pulmonar intersticial infantil; Enfermedades difusas del parénquima pulmonar en pediatría; Neumopatías intersticiales en pediatría; Niños; Paediatrics; Pediatría; chILD.
Copyright © 2021 SEPAR. Publicado por Elsevier España, S.L.U. All rights reserved.