Clinical characteristics of SARS-CoV-2-associated encephalopathy in children: Nationwide epidemiological study

J Neurol Sci. 2024 Feb 15:457:122867. doi: 10.1016/j.jns.2024.122867. Epub 2024 Jan 3.

Abstract

Objective: Severe acute respiratory syndrome coronavirus 2 (SARS-CoV-2) sometimes triggers acute encephalopathy as a serious neurological complication in children. We previously reported the clinico-radiological findings of SARS-CoV-2-associated encephalopathy. The advent of the SARS-CoV-2 omicron variant led to a marked increase in pediatric patients with coronavirus disease 2019 (COVID-19); however, epidemiological changes with acute encephalopathy according to the emergence of SARS-CoV-2 have not yet been documented. Therefore, the present study investigated epidemiological differences in SARS-CoV-2-associated encephalopathy during the BA.1/BA.2 and BA.5 predominant periods and also between SARS-CoV-2-associated and non-SARS-CoV-2-associated encephalopathy.

Methods: We conducted a nationwide survey of SARS-CoV-2-associated encephalopathy in Japanese children between June and November 2022. We compared the present results during the BA.5 predominant period and previous findings during the BA.1/BA.2 predominant period. We also compared the clinico-radiological syndromes of encephalopathy between SARS-CoV-2-associated and non-SARS-CoV-2-associated encephalopathy.

Results: Although many patients with SARS-CoV-2-associated encephalopathy in the BA.5 predominant period had seizures as their initial symptoms, no significant differences were observed in the clinical features. Patients with SARS-CoV-2-associated encephalopathy had worse outcomes than those with non-SARS-CoV-2-associated encephalopathy (p-value = 0.003). Among 103 patients with SARS-CoV-2-associated encephalopathy, 14 (13.6%) had severe types of acute encephalopathy, namely, encephalopathy with acute fulminant cerebral edema (AFCE) and hemorrhagic shock and encephalopathy syndrome (HSES). Also, 28 (27.2%) patients with SARS-CoV-2-associated encephalopathy had poor outcome: severe neurological sequelae or death. Ninety-five patients (92.2%) were not vaccinated against SARS-CoV-2.

Conclusions: In SARS-CoV-2-associated encephalopathy, high percentages of AFCE and HSES can result in poor outcomes.

Keywords: Acute encephalopathy; COVID-19; Encephalopathy with acute fulminant cerebral edema; Hemorrhagic shock and encephalopathy syndrome; SARS-CoV-2.

MeSH terms

  • Blood Coagulation Disorders*
  • Brain Diseases* / diagnostic imaging
  • Brain Diseases* / epidemiology
  • Brain Diseases* / etiology
  • COVID-19* / complications
  • COVID-19* / epidemiology
  • Child
  • Epidemiologic Studies
  • Humans
  • SARS-CoV-2
  • Shock, Hemorrhagic*

Supplementary concepts

  • SARS-CoV-2 variants
  • Hemorrhagic shock and encephalopathy syndrome