Exploring a distinct FGFR2::DLG5 rearrangement in a low-grade neuroepithelial tumor: A case report and mini-review of protein fusions in brain tumors

J Neuropathol Exp Neurol. 2024 Jun 20;83(7):567-578. doi: 10.1093/jnen/nlae040.

Abstract

We report the novel clinical presentation of a primary brain neoplasm in a 30-year-old man with a mass-like area in the anteromedial temporal lobe. Histopathological analysis revealed a low-grade neuroepithelial tumor with cytologically abnormal neurons and atypical glial cells within the cerebral cortex. Molecular analysis showed a previously undescribed FGFR2::DLG5 rearrangement. We discuss the clinical significance and molecular implications of this fusion event, shedding light on its potential impact on tumor development and patient prognosis. Additionally, an extensive review places the finding in this case in the context of protein fusions in brain tumors in general and highlights their diverse manifestations, underlying molecular mechanisms, and therapeutic implications.

Keywords: FGFR2::DLG5 fusion; Brain tumor; FGFR2; Low-grade neuroepithelial tumor.

Publication types

  • Case Reports
  • Review

MeSH terms

  • Adult
  • Brain Neoplasms* / genetics
  • Brain Neoplasms* / pathology
  • Humans
  • Male
  • Neoplasms, Neuroepithelial* / genetics
  • Neoplasms, Neuroepithelial* / pathology
  • Oncogene Proteins, Fusion / genetics
  • Receptor, Fibroblast Growth Factor, Type 2* / genetics

Substances

  • Receptor, Fibroblast Growth Factor, Type 2
  • FGFR2 protein, human
  • Oncogene Proteins, Fusion