Identification of Predictors for Progression of Scoliosis in Rett Syndrome

Dev Neurorehabil. 2024 Apr-May;27(3-4):126-133. doi: 10.1080/17518423.2024.2365794. Epub 2024 Jun 22.

Abstract

Rett syndrome is a neurodevelopmental disorder in which scoliosis is a common orthopedic complication. This explorative study aims to identify predictors for rapid progression of scoliosis in Rett syndrome to enable variable selection for future prediction model development. A univariable logistic regression model was used to identify variables that discriminate between individuals with and without rapid progression of scoliosis (>10 Cobb angle/6 months) based on multi-center data. Predictors were identified using univariable logistic regression with OR (95% CI) and AUC (95% CI). Age at inclusion, Cobb angle at baseline and epilepsy have the highest discriminative ability for rapid progression of scoliosis in Rett syndrome.

Keywords: Mecp2 mutations; Rett syndrome; prediction, neuromuscular diseases; scoliosis.

Publication types

  • Multicenter Study

MeSH terms

  • Adolescent
  • Child
  • Child, Preschool
  • Disease Progression*
  • Female
  • Humans
  • Male
  • Rett Syndrome* / complications
  • Rett Syndrome* / physiopathology
  • Scoliosis* / diagnostic imaging