Human fibroblasts from sporadic Alzheimer's disease (AD) patients show mitochondrial alterations and lysosome dysfunction

Free Radic Biol Med. 2024 Sep:222:569-578. doi: 10.1016/j.freeradbiomed.2024.07.013. Epub 2024 Jul 14.

Abstract

Mitophagy is a mechanism that maintains mitochondrial integrity and homeostasis and is thought to promote longevity and reduce the risk of age-related neurodegenerative diseases, including Alzheimer's disease (AD). Here, we investigate the abundance of mitochondrial reactive oxygen species (ROS), mitochondrial function, and mitophagy in primary fibroblasts from patients with sporadic AD (sAD) and normal healthy controls. The results show increased levels of mitochondrial ROS, changes in mitochondrial morphology, altered bioenergetic properties, and defects in autophagy, mitophagy, and lysosome-mediated degradation pathways in sAD fibroblasts relative to control fibroblasts. Interestingly, lysosome abundance and the staining of lysosomal markers remained high, while the capacity of lysosome-dependent degradation was lower in sAD fibroblasts than in controls fibroblasts. Nicotinamide riboside supplementation decreased mitochondrial ROS, while capacity for lysosomal degradation remained unchanged in sAD fibroblasts relative to healthy control fibroblasts. These findings provide insight into molecular mechanisms involving the dysregulation of lysosome and autophagy/mitophagy pathways that may contribute significantly to clinical signs and pathological features of sAD.

Keywords: Alzheimer's disease; Autophagy; Lysosome; Mitochondria; Mitophagy; Oxidative stress.

MeSH terms

  • Aged
  • Aged, 80 and over
  • Alzheimer Disease* / genetics
  • Alzheimer Disease* / metabolism
  • Alzheimer Disease* / pathology
  • Autophagy*
  • Case-Control Studies
  • Cells, Cultured
  • Female
  • Fibroblasts* / metabolism
  • Fibroblasts* / pathology
  • Humans
  • Lysosomes* / metabolism
  • Lysosomes* / pathology
  • Male
  • Middle Aged
  • Mitochondria* / metabolism
  • Mitochondria* / pathology
  • Mitophagy*
  • Niacinamide / analogs & derivatives
  • Niacinamide / pharmacology
  • Pyridinium Compounds
  • Reactive Oxygen Species* / metabolism

Substances

  • Reactive Oxygen Species
  • Niacinamide
  • Pyridinium Compounds