AL kappa amyloid in a solitary extradural lymphoma

J Neurol Neurosurg Psychiatry. 1994 Jun;57(6):751-4. doi: 10.1136/jnnp.57.6.751.

Abstract

A 68 year old man with a 10 year history of apparently benign IgM kappa paraproteinaemia presented with dysarthria, left hemiparesis, and a sensory peripheral neuropathy. A calcified right temporoparietal extradural mass was shown by scintigraphy with 123I-serum amyloid P component to contain amyloid. There were no extracranial amyloid deposits. Clinical improvement followed craniotomy and partial resection of tissue which consisted of amyloid and a mixed mononuclear cell infiltrate. The amyloid fibrils consisted of the framework 1 region of the variable domain of monoclonal kappa IV immunoglobulin light chains. There was a prominent B-cell clonal immunoglobulin gene rearrangement in the tumour tissue, supporting a diagnosis of lymphoplasmacytic lymphoma, but no sign of systemic lymphoma. Neurological state, tumour volume, and quantity of amyloid have remained static for two years after treatment with chlorambucil.

Publication types

  • Case Reports
  • Research Support, Non-U.S. Gov't

MeSH terms

  • Aged
  • Amino Acid Sequence
  • Amyloid / analysis*
  • Amyloid / chemistry
  • Chlorambucil / therapeutic use
  • Combined Modality Therapy
  • Craniotomy
  • Dysarthria / etiology
  • Gene Rearrangement, B-Lymphocyte, Light Chain
  • Hemiplegia / etiology
  • Humans
  • Immunoblotting
  • Immunoglobulin Light Chains / genetics*
  • Immunoglobulin M*
  • Immunoglobulin Variable Region
  • Iodine Radioisotopes
  • Leukocytes, Mononuclear / pathology
  • Lymphoma, B-Cell / blood
  • Lymphoma, B-Cell / chemistry*
  • Lymphoma, B-Cell / complications*
  • Lymphoma, B-Cell / diagnosis
  • Lymphoma, B-Cell / genetics
  • Lymphoma, B-Cell / surgery
  • Magnetic Resonance Imaging
  • Male
  • Molecular Sequence Data
  • Paraproteinemias / complications*
  • Peripheral Nervous System Diseases / etiology
  • Prospective Studies
  • Serum Amyloid P-Component
  • Skull Neoplasms / blood
  • Skull Neoplasms / chemistry*
  • Skull Neoplasms / complications*
  • Skull Neoplasms / diagnosis
  • Skull Neoplasms / genetics
  • Skull Neoplasms / surgery

Substances

  • Amyloid
  • Immunoglobulin Light Chains
  • Immunoglobulin M
  • Immunoglobulin Variable Region
  • Iodine Radioisotopes
  • Serum Amyloid P-Component
  • amyloid protein AL
  • Chlorambucil